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PMID: 12029458 Published · ppublish English Case Reports Journal Article Research Support, Non-U.S. Gov't

Identification of a novel mutation in the GLUT2 gene in a patient with Fanconi-Bickel syndrome presenting with neonatal diabetes mellitus and galactosaemia.

European journal of pediatrics ·Vol. 161 ·No. 6 ·2002-06-00 ·Pages 351-3

Yoo HW, Shin YL, Seo EJ, Kim GH

Abstract

We describe a patient with Fanconi-Bickel syndrome diagnosed by clinical manifestations and the identification of a novel mutation in the GLUT 2 gene. She was initially diagnosed with neonatal diabetes mellitus due to hyperglycaemia and glycosuria at 3 days of life. In addition, newborn screening for galactosaemia revealed hypergalactosaemia. Thereafter, she was managed with lactose-free milk and insulin therapy. However, she failed to grow and her liver became progressively enlarged. Her liver function deteriorated with increased prothrombin time. A liver biopsy done at age 9 months showed micronodular cirrhosis with marked fatty changes and she succumbed to hepatic failure with pneumonia at 10 months of age. DNA sequencing analysis of the GLUT 2 gene using her genomic DNA revealed a novel mutation in codon 5, lysine5 stop(K5X).

MeSH Terms
Diabetes Mellitus/blood,genetics,therapy Fanconi Syndrome/genetics,physiopathology Galactose/blood Gene Expression Regulation Glucose Transporter Type 2 Glycogen Storage Disease/genetics,pathology Humans Infant Liver/physiopathology Monosaccharide Transport Proteins/genetics Mutation
Chemicals
Glucose Transporter Type 2 Monosaccharide Transport Proteins Galactose
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Yoo Han-Wook
Department of Paediatrics, Asan Medical College of Medicine, Seoul, Korea. [email protected]
Shin Young-Lim
Seo Eul-Ju
Kim Gu-Hwan
References (9)
9 references, click to expand
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Article Info
Journal
European journal of pediatrics
Abbr.
Eur J Pediatr
ISSN
0340-6199
Published
2002-06-00
Epub
2002-00-16
Pages
351-3
Language
English
Region
Germany
NLM ID
7603873
Subset
IM
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