Abstract
During the period 1968-1974, 45 children with suspected neurodegenerative syndromes underwent brain biopsy of the right frontal lobe. The histological examination was normal in 44% and nonspecifically abnormal in 43% of the specimens. In 13% a specific histological abnormality was found, namely 3 with spongy degeneration, 1 Alexander's leucodystrophy, 1 metachromatic leucodystrophy, and 1 pachygyria. Chemical analysis by thin-layer chromatography had little to offer in this series, being specifically abnormal only in the case of metachromatic leucodystrophy and nonspecifically abnormal in 6 cases. Postoperative generalized convulsions occurred in 3 children and a mild hemiparesis contralateral to the site of biopsy was noted in one patient. Comparing the outcome of the group having histologically normal biopsies with the group having nonspecifically abnormal ones it is concluded that frontal biopsy is not of such high prognostic value as has been claimed in previous reports. Some flexibility in the choice of the biopsy site is suggested. The specimens should be examined by chemical analysis as well as electron microscope in addition to the routine histological and histochemical methods. The neurodegenerative disorders of childhood which are at present identifiable in life only by brain biopsy are listed.
MeSH Terms
Adolescent
Biopsy
Brain Chemistry
Cerebrosides/analysis
Child
Child, Preschool
Cholesterol Esters/analysis
False Negative Reactions
Female
Frontal Lobe/pathology
Humans
Infant
Male
Nervous System Diseases/diagnosis
Sphingomyelins/analysis
Chemicals
Cerebrosides
Cholesterol Esters
Sphingomyelins
Authors & Affiliations
2 authors, click to expand affiliations / ORCID
Boltshauser E
Wilson J
References (18)
18 references, click to expand
-
New variant of phenylketonuria with progressive neurological illness unresponsive to phenylalanine restriction.
Lancet. 1975 May 17;1(7916):1108-11
PMID: 49470
-
Infantile neuroaxonal dystrophy. Neuropathological and biochemical study of a case.
Arch Neurol. 1972 May;26(5):391-402
PMID: 4112690
-
Studies in myoclonus epilepsy. (Lafora body form). IV. Skeletal muscle abnormalities.
Arch Neurol. 1974 Jun;30(6):466-74
PMID: 4133238
-
Electron microscopic observations in infantile neuroaxonal dystrophy. Report of a cortical biopsy and review of the recent literature.
Arch Neurol. 1969 Jan;20(1):19-34
PMID: 4179165
-
GM3 (hematoside) sphingolipodystrophy.
N Engl J Med. 1974 Oct 31;291(18):929-31
PMID: 4213132
-
Lafora's disease: peroxisomal storage in skeletal muscle.
Neurology. 1974 Jun;24(6):531-8
PMID: 4220225
-
Subacute spongiform encephalopathy. Electron microscopic studies.
J Neurol Neurosurg Psychiatry. 1972 Dec;35(6):881-7
PMID: 4346026
-
Progressive myoclonic epilepsy with Lafora's bodies. A clinico-pathological study.
Acta Neurol Scand. 1974;50(5):537-52
PMID: 4372846
-
Progressive cerebral poliodystrophy--Alpers' disease. Disorganized giant neuronal mitochondria on electron microscopy.
J Neurol Neurosurg Psychiatry. 1972 Dec;35(6):749-55
PMID: 4647849
-
Late onset globoid cell leucodystrophy.
Brain. 1973 Dec;96(4):841-8
PMID: 4773865
-
Hallervorden-Spatz syndrome.
Arch Neurol. 1974 Jan;30(1):70-83
PMID: 4808495
-
Subacute sclerosing panencephalitis. Correlation of clinical, neurophysiologic and neuropathologic findings.
Neurology. 1974 Mar;24(3):211-8
PMID: 4855948
-
Brain biopsy in selected cases of infantile psychosis.
Acta Paedopsychiatr. 1971;38(3):90-6
PMID: 4937023
-
Giant neuronal mitochondria in a infant with microcephaly and seizure disorder.
Arch Neurol. 1969 Jan;20(1):62-72
PMID: 5763911
-
Cerebral cortical biopsy: a new vista for the pathologist.
South Med J. 1963 Apr;56:415-8
PMID: 13998248
-
SOME LIPID DISEASES OF THE BRAIN.
Proc R Soc Med. 1965 Jan;58:21-8
PMID: 14267494
-
[Value of cerebral biopsy in children with chronic cerebral diseases].
Neurochirurgie. 1967 May-Jun;13(3):385-98
PMID: 4964729
-
Diagnostic cortical biopsy; a histological and chemical study.
Lancet. 1959 Jul 11;2(7089):23-4
PMID: 13673576