Abstract
The mouse brain contains genetically distinct cells that differ with respect to chromosome number manifested as aneuploidy (Rehen et al., 2001); however, the relevance to humans is not known. Here, using double-label fluorescence in situ hybridization for the autosome chromosome 21 (chromosome 21 point probes combined with chromosome 21 "paint" probes), along with immunocytochemistry and cell sorting, we present evidence for chromosome gain and loss in the human brain. Chromosome 21 aneuploid cells constitute approximately 4% of the estimated one trillion cells in the human brain and include non-neuronal cells and postmitotic neurons identified by the neuronspecific nuclear protein marker. In comparison, human interphase lymphocytes present chromosome 21 aneuploidy rates of 0.6%. Together, these data demonstrate that human brain cells (both neurons and non-neuronal cells) can be aneuploid and that the resulting genetic mosaicism is a normal feature of the human CNS.
MeSH Terms
Adolescent
Adult
Aged
Aged, 80 and over
Aneuploidy
Cell Count/methods
Cerebral Cortex/cytology
Child
Child, Preschool
Chromosome Mapping
Chromosomes, Human, Pair 21
Female
Flow Cytometry/methods
Hippocampus/cytology
Humans
Immunohistochemistry/methods
In Situ Hybridization, Fluorescence/methods
Karyotyping/methods
Lymphocytes
Male
Middle Aged
Mosaicism
Neuroglia/metabolism
Neurons/metabolism
Phosphopyruvate Hydratase/metabolism
Postmortem Changes
Chemicals
Phosphopyruvate Hydratase
Authors & Affiliations
12 authors, click to expand affiliations / ORCID
Rehen Stevens K
Helen L. Dorris Child and Adolescent Neuropsychiatric Disorder Institute, The Scripps Research Institute, La Jolla, California 92037, USA.
Yung Yun C
McCreight Matthew P
Kaushal Dhruv
Yang Amy H
Almeida Beatriz S V
Kingsbury Marcy A
Cabral Kátia M S
McConnell Michael J
Anliker Brigitte
Fontanoz Marisa
Chun Jerold
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