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PMID: 15745943 Published · ppublish English Comparative Study Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Constitutional aneuploidy in the normal human brain.

Rehen SK, Yung YC, McCreight MP, Kaushal D, Yang AH, Almeida BS, Kingsbury MA, Cabral KM, McConnell MJ, Anliker B, Fontanoz M, Chun J

Abstract

The mouse brain contains genetically distinct cells that differ with respect to chromosome number manifested as aneuploidy (Rehen et al., 2001); however, the relevance to humans is not known. Here, using double-label fluorescence in situ hybridization for the autosome chromosome 21 (chromosome 21 point probes combined with chromosome 21 "paint" probes), along with immunocytochemistry and cell sorting, we present evidence for chromosome gain and loss in the human brain. Chromosome 21 aneuploid cells constitute approximately 4% of the estimated one trillion cells in the human brain and include non-neuronal cells and postmitotic neurons identified by the neuronspecific nuclear protein marker. In comparison, human interphase lymphocytes present chromosome 21 aneuploidy rates of 0.6%. Together, these data demonstrate that human brain cells (both neurons and non-neuronal cells) can be aneuploid and that the resulting genetic mosaicism is a normal feature of the human CNS.

MeSH Terms
Adolescent Adult Aged Aged, 80 and over Aneuploidy Cell Count/methods Cerebral Cortex/cytology Child Child, Preschool Chromosome Mapping Chromosomes, Human, Pair 21 Female Flow Cytometry/methods Hippocampus/cytology Humans Immunohistochemistry/methods In Situ Hybridization, Fluorescence/methods Karyotyping/methods Lymphocytes Male Middle Aged Mosaicism Neuroglia/metabolism Neurons/metabolism Phosphopyruvate Hydratase/metabolism Postmortem Changes
Chemicals
Phosphopyruvate Hydratase
Authors & Affiliations
12 authors, click to expand affiliations / ORCID
Rehen Stevens K
Helen L. Dorris Child and Adolescent Neuropsychiatric Disorder Institute, The Scripps Research Institute, La Jolla, California 92037, USA.
Yung Yun C
McCreight Matthew P
Kaushal Dhruv
Yang Amy H
Almeida Beatriz S V
Kingsbury Marcy A
Cabral Kátia M S
McConnell Michael J
Anliker Brigitte
Fontanoz Marisa
Chun Jerold
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Article Info
Journal
The Journal of neuroscience : the official journal of the Society for Neuroscience
Abbr.
J Neurosci
ISSN
1529-2401
Published
2005-03-02
Pages
2176-80
Language
English
Region
United States
NLM ID
8102140
PMCID
PMC6726097
Subset
IM
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