Abstract
We detected a germ-line mutation of the p53 gene in a patient with a malignant ependymoma of the posterior fossa. This mutation, which was found at codon 242, resulted in an amino acid substitution in a highly conserved site of exon 7 of the p53 gene; the same mutation was found in both the germ-line and the tumor tissue. This is the most common region of previously described somatic p53 mutations in tumor specimens and of the germ-line p53 mutations in patients with the Li-Fraumeni cancer syndrome. Evaluation of the patient's family revealed several direct maternal and paternal relatives who had died at a young age from different types of cancer. The association of a germ-line p53 mutation with an intracranial malignancy and a strong family history of cancer suggests that p53 gene mutations predispose a person to malignancy and, like retinoblastoma mutations, may be inherited.
MeSH Terms
Amino Acid Sequence
Animals
Base Sequence
Brain Neoplasms/genetics
Child, Preschool
Codon/genetics
DNA, Neoplasm/blood,genetics,isolation & purification
Ependymoma/genetics
Female
Genes, Tumor Suppressor
Humans
Leukocytes/physiology
Male
Molecular Sequence Data
Mutation
Oligonucleotide Probes
Pedigree
Polymerase Chain Reaction/methods
Polymorphism, Restriction Fragment Length
Sequence Homology, Nucleic Acid
Tumor Suppressor Protein p53/genetics
Chemicals
Codon
DNA, Neoplasm
Oligonucleotide Probes
Tumor Suppressor Protein p53
Authors & Affiliations
6 authors, click to expand affiliations / ORCID
Metzger A K
Brain Tumor Research Center, University of California, San Francisco 94143.
Sheffield V C
Duyk G
Daneshvar L
Edwards M S
Cogen P H
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