Home LiteratureArticle Details
PMID: 1770528 Published · ppublish English Case Reports Journal Article

Alpha thalassaemia/mental retardation syndrome (non-deletional type): report of a family supporting X linked inheritance.

Journal of medical genetics ·Vol. 28 ·No. 11 ·1991-11-00 ·Pages 734-7

Cole TR, May A, Hughes HE

Abstract

In 1990 the existence of an X linked form of the alpha thalassaemia/mental retardation syndrome was postulated after the description of six isolated cases who were all cytogenetically male. The segregation pattern in the family described here supports X linked inheritance. The clinical details of our two patients are remarkably similar to the previously delineated phenotype. In addition, renal anomalies were identified in one patient, but their significance will remain uncertain until further cases have been assessed. Affected subjects could be identified by the presence of Hb H inclusions, and were also noted to have abnormalities of several haematological indices. Examination of blood from obligatory carriers in this family suggests that Hb H inclusions are not an invariable finding and that haematological indices appear to be unaffected by the condition in female heterozygotes.

MeSH Terms
Adolescent Adult Genetic Linkage Hemoglobin H/genetics Humans Intellectual Disability/complications,genetics Male Pedigree Syndrome Thalassemia/complications,genetics X Chromosome
Chemicals
Hemoglobin H
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Cole T R
Institute of Medical Genetics, University Hospital of Wales, Heath Park, Cardiff.
May A
Hughes H E
References (6)
6 references, click to expand
  1. Hemoglobin H disease and mental retardation: a new syndrome or a remarkable coincidence?
    N Engl J Med. 1981 Sep 10;305(11):607-12 PMID: 6267462
  2. Occurrence of the alpha thalassaemia-mental retardation syndrome (non-deletional type) in an Australian male.
    J Med Genet. 1990 Sep;27(9):577-81 PMID: 2231651
  3. Iron overload in mild sideroblastic anaemias.
    Lancet. 1983 Feb 19;1(8321):375-8 PMID: 6130377
  4. Mental retardation, distinct facial changes, short stature, obesity, and hypogonadism: a new X-linked mental retardation syndrome.
    Am J Med Genet. 1988 Dec;31(4):741-51 PMID: 3239563
  5. Clinical features and molecular analysis of the alpha thalassemia/mental retardation syndromes. II. Cases without detectable abnormality of the alpha globin complex.
    Am J Hum Genet. 1990 Jun;46(6):1127-40 PMID: 2339705
  6. A family study of congenital X linked sideroblastic anaemia.
    J Med Genet. 1990 Jan;27(1):26-8 PMID: 2308152
Article Info
Journal
Journal of medical genetics
Abbr.
J Med Genet
ISSN
0022-2593
Published
1991-11-00
Pages
734-7
Language
English
Region
England
NLM ID
2985087R
PMCID
PMC1017106
Subset
IM
Analysis Services
Analysis Services

Contact

No. 2 Wenbo Road, Zhangqiu District, Jinan, Shandong

Qilu Normal University · Genelibs Bioinformatics Lab

750 Shunhua Rd, Jinan

2F, Bldg F, University Science Park

Tel: 0531-88819269

WeChat Official Account

Follow our WeChat subscription account for real-time updates and the latest in medical and biological research.


Business Email

E-mail: [email protected]