Abstract
There is substantial evidence that cerebrospinal fluid (CSF) levels of both Abeta42 and tau/ptau are promising biomarkers for Alzheimer's disease (AD). We show that both Abeta and tau exhibit more than 10-fold interindividual variation in CSF levels suggesting that these biomarkers may also be effectively used as endophenotypes for genetic studies of AD. To test the role of common variation in the gene encoding microtubule associated protein tau (MAPT) in influencing CSF tau/ptau levels, we genotyped 21 MAPT single nucleotide polymorphisms (SNPs) in 313 individuals and tested for association with CSF tau/ptau levels. We identified alleles of several SNPs that show association with increased CSF tau/ptau levels. When CSF Abeta42 levels were used to stratify the sample into those with and without likely Abeta deposition in the brain the association was only observed in individuals with evidence of Abeta deposition. This association was replicated in an independent CSF series. When these SNPs were evaluated in a late-onset AD case control series the alleles associated with higher CSF tau/ptau were associated with an earlier age at onset but had no effect on risk for AD. In vivo gene expression studies show that these alleles are associated with increased MAPT mRNA levels in individuals with evidence of brain Abeta deposition. This endophenotype-based approach provides evidence for a gene (MAPT SNPs)-physiological environment (Abeta deposition) interaction that places changes in CSF tau after Abeta deposition and suggest that this interaction predisposes for the development of tauopathy and accelerated disease progression.
MeSH Terms
Adult
Age of Onset
Aged
Aged, 80 and over
Alleles
Amyloid beta-Peptides/metabolism
Female
Gene Expression Regulation
Haplotypes
Homozygote
Humans
Male
Middle Aged
Polymorphism, Single Nucleotide/genetics
RNA, Messenger/genetics,metabolism
Survival Analysis
tau Proteins/cerebrospinal fluid,genetics
Chemicals
Amyloid beta-Peptides
MAPT protein, human
RNA, Messenger
tau Proteins
Authors & Affiliations
12 authors, click to expand affiliations / ORCID
Kauwe John S K
Department of Psychiatry, Washington University School of Medicine, St. Louis, MO 63110, USA.
Cruchaga Carlos
Mayo Kevin
Fenoglio Chiara
Bertelsen Sarah
Nowotny Petra
Galimberti Daniela
Scarpini Elio
Morris John C
Fagan Anne M
Holtzman David M
Goate Alison M
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