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PMID: 2029917 Published · ppublish English Journal Article

Renal tubular dysfunction in methylmalonic acidaemia.

European journal of pediatrics ·Vol. 150 ·No. 4 ·1991-02-00 ·Pages 259-63

D'Angio CT, Dillon MJ, Leonard JV

Abstract

Renal tubular function was assessed in seven patients with methylmalonic acidaemia not responsive to vitamin B12. Five patients failed to concentrate their urine normally and in these patients the glomerular filtration rate was also reduced. Fractional excretion of sodium was increased in four patients, fractional excretion of potassium in one patient and in three there was a decreased tubular reabsorption of phosphate. Although possibly representing primary tubular damage these findings were thought to be consistent with adaptive changes secondary to the reduced glomerular filtration rate. Two patients had evidence of a defect of urinary acidification and several had a degree of hyporeninaemic hypoaldosteronism suggesting type 4 renal tubular acidosis. In one patient with a mild variant no renal disease was detected. Decreased renal function and tubular abnormalities were common in patients with methylmalonic acidaemia. It is likely that they are linked and essentially secondary to the tubulo-interstitial nephritis that is histologically demonstrable on renal biopsy. The failure of urinary concentrating ability and the disturbed urine acidification will contribute to the metabolic derangement during episodes of decompensation.

MeSH Terms
Acidosis, Renal Tubular/complications,physiopathology Child Child, Preschool Glomerular Filtration Rate/physiology Humans Hydrogen-Ion Concentration Kidney Concentrating Ability/physiology Kidney Tubules/physiopathology Metabolism, Inborn Errors/complications,drug therapy,physiopathology Methylmalonic Acid/blood,urine Potassium/urine Sodium/urine Urine/chemistry Vitamin B 12/therapeutic use
Chemicals
Methylmalonic Acid Sodium Vitamin B 12 Potassium
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
D'Angio C T
Department of Child Health, Hospital for Sick Children, London, UK.
Dillon M J
Leonard J V
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Article Info
Journal
European journal of pediatrics
Abbr.
Eur J Pediatr
ISSN
0340-6199
Published
1991-02-00
Pages
259-63
Language
English
Region
Germany
NLM ID
7603873
Subset
IM
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