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PMID: 21030649 Published · ppublish English Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, Non-P.H.S.

Diversity of human copy number variation and multicopy genes.

Science (New York, N.Y.) ·Vol. 330 ·No. 6004 ·2010-10-29 ·Pages 641-6

Sudmant PH, Kitzman JO, Antonacci F, Alkan C, Malig M, Tsalenko A, Sampas N, Bruhn L, Shendure J, 1000 Genomes Project, Eichler EE

Abstract

Copy number variants affect both disease and normal phenotypic variation, but those lying within heavily duplicated, highly identical sequence have been difficult to assay. By analyzing short-read mapping depth for 159 human genomes, we demonstrated accurate estimation of absolute copy number for duplications as small as 1.9 kilobase pairs, ranging from 0 to 48 copies. We identified 4.1 million "singly unique nucleotide" positions informative in distinguishing specific copies and used them to genotype the copy and content of specific paralogs within highly duplicated gene families. These data identify human-specific expansions in genes associated with brain development, reveal extensive population genetic diversity, and detect signatures consistent with gene conversion in the human species. Our approach makes ~1000 genes accessible to genetic studies of disease association.

MeSH Terms
Chromosome Mapping DNA Copy Number Variations Databases, Nucleic Acid Evolution, Molecular Female Gene Conversion Gene Dosage Gene Duplication Gene Frequency Genes, Duplicate Genetic Variation Genome, Human Genomics/methods Genotype Haplotypes Humans Male Polymorphism, Single Nucleotide Racial Groups/genetics Sequence Analysis, DNA
Authors & Affiliations
11 authors, click to expand affiliations / ORCID
Sudmant Peter H
Department of Genome Sciences, University of Washington School of Medicine, Seattle, WA 98195, USA.
Kitzman Jacob O
Antonacci Francesca
Alkan Can
Malig Maika
Tsalenko Anya
Sampas Nick
Bruhn Laurakay
Shendure Jay
1000 Genomes Project
Eichler Evan E
Investigators
552 investigators, click to expand
Altshuler David L
Durbin Richard M
Abecasis Gonçalo R
Bentley David R
Chakravarti Aravinda
Clark Andrew G
Collins Francis S
De La Vega Francisco M
Donnelly Peter
Egholm Michael
Flicek Paul
Gabriel Stacey B
Gibbs Richard A
Knoppers Bartha M
Lander Eric S
Lehrach Hans
Mardis Elaine R
McVean Gil A
Nickerson Debbie A
Peltonen Leena
Schafer Alan J
Sherry Stephen T
Wang Jun
Wilson Richard K
Gibbs Richard A
Deiros David
Metzker Mike
Muzny Donna
Reid Jeff
Wheeler David
Wang Jun
Li Jingxiang
Jian Min
Li Guoqing
Li Ruiqiang
Liang Huiqing
Tian Geng
Wang Bo
Wang Jian
Wang Wei
Yang Huanming
Zhang Xiuqing
Zheng Huisong
Lander Eric S
Altshuler David L
Ambrogio Lauren
Bloom Toby
Cibulskis Kristian
Fennell Tim J
Gabriel Stacey B
Jaffe David B
Shefler Erica
Sougnez Carrie L
Bentley David R
Gormley Niall
Humphray Sean
Kingsbury Zoya
Koko-Gonzales Paula
Stone Jennifer
McKernan Kevin J
Costa Gina L
Ichikawa Jeffry K
Lee Clarence C
Sudbrak Ralf
Lehrach Hans
Borodina Tatiana A
Dahl Andreas
Davydov Alexey N
Marquardt Peter
Mertes Florian
Nietfeld Wilfiried
Rosenstiel Philip
Schreiber Stefan
Soldatov Aleksey V
Timmermann Bernd
Tolzmann Marius
Egholm Michael
Affourtit Jason
Ashworth Dana
Attiya Said
Bachorski Melissa
Buglione Eli
Burke Adam
Caprio Amanda
Celone Christopher
Clark Shauna
Conners David
Desany Brian
Gu Lisa
Guccione Lorri
Kao Kalvin
Kebbel Andrew
Knowlton Jennifer
Labrecque Matthew
McDade Louise
Mealmaker Craig
Minderman Melissa
Nawrocki Anne
Niazi Faheem
Pareja Kristen
Ramenani Ravi
Riches David
Song Wanmin
Turcotte Cynthia
Wang Shally
Mardis Elaine R
Wilson Richard K
Dooling David
Fulton Lucinda
Fulton Robert
Weinstock George
Durbin Richard M
Burton John
Carter David M
Churcher Carol
Coffey Alison
Cox Anthony
Palotie Aarno
Quail Michael
Skelly Tom
Stalker James
Swerdlow Harold P
Turner Daniel
De Witte Anniek
Giles Shane
Gibbs Richard A
Wheeler David
Bainbridge Matthew
Challis Danny
Sabo Aniko
Yu Fuli
Yu Jin
Wang Jun
Fang Xiaodong
Guo Xiaosen
Li Ruiqiang
Li Yingrui
Luo Ruibang
Tai Shuaishuai
Wu Honglong
Zheng Hancheng
Zheng Xiaole
Zhou Yan
Li Guoqing
Wang Jian
Yang Huanming
Marth Gabor T
Garrison Erik P
Huang Weichun
Indap Amit
Kural Deniz
Lee Wan-Ping
Leong Wen Fung
Quinlan Aaron R
Stewart Chip
Stromberg Michael P
Ward Alistair N
Wu Jiantao
Lee Charles
Mills Ryan E
Shi Xinghua
Daly Mark J
DePristo Mark A
Altshuler David L
Ball Aaron D
Banks Eric
Bloom Toby
Browning Brian L
Cibulskis Kristian
Fennell Tim J
Garimella Kiran V
Grossman Sharon R
Handsaker Robert E
Hanna Matt
Hartl Chris
Jaffe David B
Kernytsky Andrew M
Korn Joshua M
Li Heng
Maguire Jared R
McCarroll Steven A
McKenna Aaron
Nemesh James C
Philippakis Anthony A
Poplin Ryan E
Price Alkes
Rivas Manuel A
Sabeti Pardis C
Schaffner Stephen F
Shefler Erica
Shlyakhter Ilya A
Cooper David N
Ball Edward V
Mort Matthew
Phillips Andrew D
Stenson Peter D
Sebat Jonathan
Makarov Vladimir
Ye Kenny
Yoon Seungtai C
Bustamante Carlos D
Clark Andrew G
Boyko Adam
Degenhardt Jeremiah
Gravel Simon
Gutenkunst Ryan N
Kaganovich Mark
Keinan Alon
Lacroute Phil
Ma Xin
Reynolds Andy
Clarke Laura
Flicek Paul
Cunningham Fiona
Herrero Javier
Keenen Stephen
Kulesha Eugene
Leinonen Rasko
McLaren William M
Radhakrishnan Rajesh
Smith Richard E
Zalunin Vadim
Zheng-Bradley Xiangqun
Korbel Jan O
Stütz Adrian M
Humphray Sean
Bauer Markus
Cheetham R Keira
Cox Tony
Eberle Michael
James Terena
Kahn Scott
Murray Lisa
Chakravarti Aravinda
Ye Kai
De La Vega Francisco M
Fu Yutao
Hyland Fiona C L
Manning Jonathan M
McLaughlin Stephen F
Peckham Heather E
Sakarya Onur
Sun Yongming A
Tsung Eric F
Batzer Mark A
Konkel Miriam K
Walker Jerilyn A
Sudbrak Ralf
Albrecht Marcus W
Amstislavskiy Vyacheslav S
Herwig Ralf
Parkhomchuk Dimitri V
Sherry Stephen T
Agarwala Richa
Khouri Hoda M
Morgulis Aleksandr O
Paschall Justin E
Phan Lon D
Rotmistrovsky Kirill E
Sanders Robert D
Shumway Martin F
Xiao Chunlin
McVean Gil A
Auton Adam
Iqbal Zamin
Lunter Gerton
Marchini Jonathan L
Moutsianas Loukas
Myers Simon
Tumian Afidalina
Desany Brian
Knight James
Winer Roger
Craig David W
Beckstrom-Sternberg Steve M
Christoforides Alexis
Kurdoglu Ahmet A
Pearson John V
Sinari Shripad A
Tembe Waibhav D
Haussler David
Hinrichs Angie S
Katzman Sol J
Kern Andrew
Kuhn Robert M
Przeworski Molly
Hernandez Ryan D
Howie Bryan
Kelley Joanna L
Melton S Cord
Abecasis Gonçalo R
Li Yun
Anderson Paul
Blackwell Tom
Chen Wei
Cookson William O
Ding Jun
Kang Hyun Min
Lathrop Mark
Liang Liming
Moffatt Miriam F
Scheet Paul
Sidore Carlo
Snyder Matthew
Zhan Xiaowei
Zöllner Sebastian
Awadalla Philip
Casals Ferran
Idaghdour Youssef
Keebler John
Stone Eric A
Zilversmit Martine
Jorde Lynn
Xing Jinchuan
Eichler Evan E
Aksay Gozde
Alkan Can
Hajirasouliha Iman
Hormozdiari Fereydoun
Kidd Jeffrey M
Sahinalp S Cenk
Sudmant Peter H
Mardis Elaine R
Chen Ken
Chinwalla Asif
Ding Li
Koboldt Daniel C
McLellan Mike D
Dooling David
Weinstock George
Wallis John W
Wendl Michael C
Zhang Qunyuan
Durbin Richard M
Albers Cornelis A
Ayub Qasim
Balasubramaniam Senduran
Barrett Jeffrey C
Carter David M
Chen Yuan
Conrad Donald F
Danecek Petr
Dermitzakis Emmanouil T
Hu Min
Huang Ni
Hurles Matt E
Jin Hanjun
Jostins Luke
Keane Thomas M
Le Si Quang
Lindsay Sarah
Long Quan
MacArthur Daniel G
Montgomery Stephen B
Parts Leopold
Stalker James
Tyler-Smith Chris
Walter Klaudia
Zhang Yujun
Gerstein Mark B
Snyder Michael
Abyzov Alexej
Balasubramanian Suganthi
Bjornson Robert
Du Jiang
Grubert Fabian
Habegger Lukas
Haraksingh Rajini
Jee Justin
Khurana Ekta
Lam Hugo Y K
Leng Jing
Mu Xinmeng Jasmine
Urban Alexander E
Zhang Zhengdong
Li Yingrui
Luo Ruibang
Marth Gabor T
Garrison Erik P
Kural Deniz
Quinlan Aaron R
Stewart Chip
Stromberg Michael P
Ward Alistair N
Wu Jiantao
Lee Charles
Mills Ryan E
Shi Xinghua
McCarroll Steven A
Banks Eric
DePristo Mark A
Handsaker Robert E
Hartl Chris
Korn Joshua M
Li Heng
Nemesh James C
Sebat Jonathan
Makarov Vladimir
Ye Kenny
Yoon Seungtai C
Degenhardt Jeremiah
Kaganovich Mark
Clarke Laura
Smith Richard E
Zheng-Bradley Xiangqun
Korbel Jan O
Humphray Sean
Cheetham R Keira
Eberle Michael
Kahn Scott
Murray Lisa
Ye Kai
De La Vega Francisco M
Fu Yutao
Peckham Heather E
Sun Yongming A
Batzer Mark A
Konkel Miriam K
Walker Jerilyn A
Xiao Chunlin
Iqbal Zamin
Desany Brian
Blackwell Tom
Snyder Matthew
Xing Jinchuan
Eichler Evan E
Aksay Gozde
Alkan Can
Hajirasouliha Iman
Hormozdiari Fereydoun
Kidd Jeffrey M
Chen Ken
Chinwalla Asif
Ding Li
McLellan Mike D
Wallis John W
Hurles Matt E
Conrad Donald F
Walter Klaudia
Zhang Yujun
Gerstein Mark B
Snyder Michael
Abyzov Alexej
Du Jiang
Grubert Fabian
Haraksingh Rajini
Jee Justin
Khurana Ekta
Lam Hugo Y K
Leng Jing
Mu Xinmeng Jasmine
Urban Alexander E
Zhang Zhengdong
Gibbs Richard A
Bainbridge Matthew
Challis Danny
Coafra Cristian
Dinh Huyen
Kovar Christie
Lee Sandy
Muzny Donna
Nazareth Lynne
Reid Jeff
Sabo Aniko
Yu Fuli
Yu Jin
Marth Gabor T
Garrison Erik P
Indap Amit
Leong Wen Fung
Quinlan Aaron R
Stewart Chip
Ward Alistair N
Wu Jiantao
Cibulskis Kristian
Fennell Tim J
Gabriel Stacey B
Garimella Kiran V
Hartl Chris
Shefler Erica
Sougnez Carrie L
Wilkinson Jane
Clark Andrew G
Gravel Simon
Grubert Fabian
Clarke Laura
Flicek Paul
Smith Richard E
Zheng-Bradley Xiangqun
Sherry Stephen T
Khouri Hoda M
Paschall Justin E
Shumway Martin F
Xiao Chunlin
McVean Gil A
Katzman Sol J
Abecasis Gonçalo R
Blackwell Tom
Mardis Elaine R
Dooling David
Fulton Lucinda
Fulton Robert
Koboldt Daniel C
Durbin Richard M
Balasubramaniam Senduran
Coffey Allison
Keane Thomas M
MacArthur Daniel G
Palotie Aarno
Scott Carol
Stalker James
Tyler-Smith Chris
Gerstein Mark B
Balasubramanian Suganthi
Chakravarti Aravinda
Knoppers Bartha M
Peltonen Leena
Abecasis Gonçalo R
Bustamante Carlos D
Gharani Neda
Gibbs Richard A
Jorde Lynn
Kaye Jane S
Kent Alastair
Li Taosha
McGuire Amy L
McVean Gil A
Ossorio Pilar N
Rotimi Charles N
Su Yeyang
Toji Lorraine H
Tyler-Smith Chris
Brooks Lisa D
Felsenfeld Adam L
McEwen Jean E
Abdallah Assya
Juenger Christopher R
Clemm Nicholas C
Collins Francis S
Duncanson Audrey
Green Eric D
Guyer Mark S
Peterson Jane L
Schafer Alan J
Abecasis Gonçalo R
Altshuler David L
Auton Adam
Brooks Lisa D
Durbin Richard M
Gibbs Richard A
Hurles Matt E
McVean Gil A
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Article Info
Journal
Science (New York, N.Y.)
Abbr.
Science
ISSN
1095-9203
Published
2010-10-29
Pages
641-6
Language
English
Region
United States
NLM ID
0404511
PMCID
PMC3020103
Subset
IM
Grants
NHGRI NIH HHS · P01 HG004120-03 · United States
NHGRI NIH HHS · U54 HG003067 · United States
NHGRI NIH HHS · U54 HG003273 · United States
NHGRI NIH HHS · HG004120 · United States
Howard Hughes Medical Institute · United States
Wellcome Trust · 085532 · United Kingdom
NHGRI NIH HHS · P01 HG004120 · United States
Databases
GEO
Corrections
CommentIn
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