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PMID: 2878115 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

DNA analysis for ornithine transcarbamylase deficiency.

Journal of inherited metabolic disease ·Vol. 9 Suppl 1 ·1986-00-00 ·Pages 49-57

Rozen R, Fox JE, Hack AM, Fenton WA, Horwich AL, Rosenberg LE

Abstract

We have utilized the Southern blotting technique to analyse genomic DNA from males with ornithine transcarbamylase (OTC) deficiency and their families. Using a nearly full-length human cDNA probe, we have identified 3 patients with deletions at this locus and have characterized 4 different restriction fragment length polymorphisms that can be used as linkage markers for the OTC mutation. These polymorphisms occur at sufficiently high frequencies so as to enable us to distinguish the two X-chromosomes in approximately 80% of OTC carriers. As a direct consequence of these findings, prenatal diagnosis and carrier assessment can be offered to a large fraction of families at risk for OTC deficiency.

MeSH Terms
Chromosome Deletion DNA/genetics Female Genetic Linkage Genetic Markers Heterozygote Humans Male Mutation Ornithine Carbamoyltransferase/genetics Ornithine Carbamoyltransferase Deficiency Disease Pedigree Polymorphism, Restriction Fragment Length X Chromosome
Chemicals
Genetic Markers DNA Ornithine Carbamoyltransferase
Authors & Affiliations
6 authors, click to expand affiliations / ORCID
Rozen R
Fox J E
Hack A M
Fenton W A
Horwich A L
Rosenberg L E
References (11)
11 references, click to expand
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Article Info
Journal
Journal of inherited metabolic disease
Abbr.
J Inherit Metab Dis
ISSN
0141-8955
Published
1986-00-00
Pages
49-57
Language
English
Region
United States
NLM ID
7910918
Subset
IM
Grants
NIGMS NIH HHS · GM 32156 · United States
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