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PMID: 3947601 Published · ppublish English Case Reports Journal Article Research Support, Non-U.S. Gov't

Primary vitreoretinal dysplasia resembling Norrie's disease in a female: association with X autosome chromosomal translocation.

The British journal of ophthalmology ·Vol. 70 ·No. 1 ·1986-01-00 ·Pages 64-71

Ohba N, Yamashita T

Abstract

A female infant with the typical clinical and histopathological features of vitreoretinal dysplasia is described. She had an apparently balanced reciprocal chromosomal translocation 46XX,t(X;10) with the X chromosome breakpoint being on the short arm. Since the parents' karyotypes were normal, it is most plausible that a de novo chromosomal translocation disrupted the vitreoretinal dysplasia gene itself. The severe clinical symptoms of this heterozygous female patient were explained by non-random X inactivation. She may have had Norrie's disease, an X linked recessive disorder due to an X autosome translocation.

MeSH Terms
Female Humans Infant, Newborn Karyotyping Retina/abnormalities Retinal Detachment/pathology Sex Chromosome Aberrations/genetics,pathology Translocation, Genetic Vitreous Body/abnormalities X Chromosome
Authors & Affiliations
2 authors, click to expand affiliations / ORCID
Ohba N
Yamashita T
References (11)
11 references, click to expand
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Article Info
Journal
The British journal of ophthalmology
Abbr.
Br J Ophthalmol
ISSN
0007-1161
Published
1986-01-00
Pages
64-71
Language
English
Region
England
NLM ID
0421041
PMCID
PMC1040906
Subset
IM
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