Abstract
Total lactosyl ceramide beta-galactosidase (LC) activity from normal and pathologic human leukocytes and tissues was subdivided into LC I (EC 3.2.1.46) and LC II (EC 3.2.1.23) activity by means of specific inhibition of LC II with 5 mM p-nitrophenyl-beta-D-galactoside (Ki = 1.5 mM). In globoid-cell leudodystrophy, inhibition of total LC was nearly complete (only LC II is active), whereas in GM1-gangliosidosis Type 1, very little inhibition was found (only LC I is actict). Total LC activity was not significantly low in either of the diseases, which have different genetic origins. The ratio of LC I to LC II activity may display remarkable genetic variation in normal probands.
MeSH Terms
Child
Child, Preschool
Galactosidases/deficiency
Galactosylceramidase/blood,deficiency
Gangliosidoses/enzymology
Humans
Infant
Lactose Intolerance
Leukocytes/enzymology
Leukodystrophy, Globoid Cell/enzymology
beta-Galactosidase/blood
Chemicals
Galactosidases
beta-Galactosidase
Galactosylceramidase
Authors & Affiliations
1 authors, click to expand affiliations / ORCID
Harzer K
References (10)
10 references, click to expand
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