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PMID: 4815083 Published · ppublish English Journal Article

Detection of the carrier state in combined immunodeficiency disease associated with adenosine deaminase deficiency.

The Journal of clinical investigation ·Vol. 53 ·No. 4 ·1974-04-00 ·Pages 1194-6

Scott CR, Chen SH, Giblett ER

Abstract

A large pedigree containing a child with severe combined immunodeficiency disease (CID) associated with adenosine deaminase (ADA) deficiency was investigated to ascertain if heterozygotes could be detected by measuring red cell ADA activity. 9 of 17 individuals in three generations who were at risk for being heterozygous had decreased red cell ADA activity. This genetic information establishes one form of CID as an autosomal recessive disorder. The identified heterozygote population had a mean ADA value of 19.2 U/g hemoglobin (0.95 confidence interval; 14.0 to 24.4 U/g hemoglobin), which was approximately one-half the mean, 36.1 U/g hemoglobin, of a randomly selected control population (0.95 confidence interval; 22.5-58.1 U/g hemoglobin). Statistical comparisons of the heterozygotes to the normal population indicates that within a high-risk family heterozygotes may be identified with 90% confidence.

MeSH Terms
Adenosine Adult Aminohydrolases/blood Deficiency Diseases/complications Erythrocytes/enzymology Female Hemoglobins Heterozygote Humans Immunologic Deficiency Syndromes/complications,genetics Male Middle Aged Pedigree
Chemicals
Hemoglobins Aminohydrolases Adenosine
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Scott C R
Chen S H
Giblett E R
References (11)
11 references, click to expand
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Article Info
Journal
The Journal of clinical investigation
Abbr.
J Clin Invest
ISSN
0021-9738
Published
1974-04-00
Pages
1194-6
Language
English
Region
United States
NLM ID
7802877
PMCID
PMC333106
Subset
IM
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