Abstract
Hypogammaglobulinemia due to a new pathophysiological mechanism was studied in a patient with Sjögren's syndrome, a monoclonal IgM and a mixed (IgM-IgG) cryoglobulinemia. The IgM (IgMdk) component of the cryogel possessed light chains of lambda-type with highly restricted electrophoretic mobility analagous to those of a Waldenström's macroglobulin. IgMdk reacted specifically with native IgG, with IgG subclasses 1, 2, and 4, and with the Fc piece of IgG to form a cryogel. Serum concentrations of IgG 1, 2, and 4 were 10% of normal, whereas the IgG3 level was slightly increased and the IgM level was markedly increased. Viscosity and analytical ultracentrifugation studies with the purified mixed cryogel (IgM-LgG) indicated soluble complex formation over a temperature range (36-38 degrees C) attainable in vivo. Immunoglobulin turnover studies revealed a markedly elevated rate of IgM synthesis with a normal survival of IgM, IgA, and IgE. IgG3, which failed to form complexes with IgMdk at body temperature, had a normal synthetic rate and survival. In contrast, the other IgG subclasses showed reduced synthesis and shortened survival. These studies are the first indicating a short survival of some IgG subclasses with a normal survival of another. The hypogammaglobulinemia appears to be due in part to a new mechanism of accelerated protein catabolism: The rapid elimination of IgG due to its interaction with an IgG-reactive monoclonal IgM.
MeSH Terms
Agammaglobulinemia/metabolism
Aged
Blood Viscosity
Electrophoresis, Disc
Female
Humans
Immunochemistry
Immunodiffusion
Immunoelectrophoresis
Immunoglobulin G/metabolism
Immunoglobulin M/metabolism
Immunoglobulins/metabolism
Plasma Volume
Serum Albumin, Radio-Iodinated/metabolism
Sjogren's Syndrome/metabolism
Ultracentrifugation
Chemicals
Immunoglobulin G
Immunoglobulin M
Immunoglobulins
Serum Albumin, Radio-Iodinated
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Waldmann T A
Johnson J S
Talal N
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