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PMID: 6298775 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Identification and characterization of cells deficient in the mannose 6-phosphate receptor: evidence for an alternate pathway for lysosomal enzyme targeting.

Gabel CA, Goldberg DE, Kornfeld S

Abstract

Newly synthesized lysosomal enzymes acquire phosphomannosyl units, which allow binding of the enzymes to the mannose 6-phosphate receptor and subsequent translocation to lysosomes. In some cell types, this sequence of events is necessary for the delivery of these enzymes to lysosomes. Using a slime mold lysosomal hydrolase as a probe, we have identified three murine cell lines that lack the receptor and one line that contains very low (3%) receptor activity. Each of these lines synthesizes the mannose 6-phosphate recognition marker on its lysosomal enzymes, but, unlike cell lines with high levels of receptor, the cells accumulate oligosaccharides containing phosphomonoesters. The receptor-deficient lines possess high levels of intracellular acid hydrolase activity, which is contained in dense granules characteristic of lysosomes. The data suggest that intracellular mechanisms independent of the mannose 6-phosphate receptor must exist in some cells for the delivery of acid hydrolases to lysosomal organelles.

MeSH Terms
Animals Cell Compartmentation Cells, Cultured Cricetinae Hexosephosphates/metabolism Intracellular Membranes/metabolism Lysosomes/enzymology Mannosephosphates/metabolism Mice Oligosaccharides/metabolism Phosphorylation Receptor, IGF Type 2 Receptors, Cell Surface/metabolism
Chemicals
Hexosephosphates Mannosephosphates Oligosaccharides Receptor, IGF Type 2 Receptors, Cell Surface
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Gabel C A
Goldberg D E
Kornfeld S
References (28)
28 references, click to expand
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Article Info
Journal
Proceedings of the National Academy of Sciences of the United States of America
Abbr.
Proc Natl Acad Sci U S A
ISSN
0027-8424
Published
1983-02-00
Pages
775-9
Language
English
Region
United States
NLM ID
7505876
PMCID
PMC393462
Subset
IM
Grants
NIGMS NIH HHS · 5T05GM02016 · United States
NIGMS NIH HHS · GM 07200 · United States
NCI NIH HHS · R01 CA08759 · United States
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