Abstract
The authors discuss the clinical and cytogenetic problems raised in two new cases of X-chromosome translocations. The first case involves a child who presented marked malformations at age 3 months. Chromosome analysis revealed the presence of a translocation between a 22 and X chromosome resulting in partial X monosomy and partial trisomy 22: 46,X,der(X),t(X:22)(q112;q13)mat. The balanced translocation form was detected in the mother. Dynamic study after 5-Brdu treatment revealed inactivation of the translocated X chromosome in the proband, while in the mother the normal X chromosome was inactivated. In addition to magnesium dependent hypocalcemia resulting from a specific absorption anomaly, Case 2 presented discrete malformations and psychomotor retardation. Chromosome analysis revealed an apparently balanced translocation between a 9 and X chromosome: 46,X,t(9;X)(q12;p22). Treatment with 5-Brdu demonstrated that the translocated X chromosome was inactivated but that inactivation did not extend to the translocated part of chromosome 9. Finally, a pericentric inversion of a 9 chromosome was detected in the father, grandfather, and brother of the proband.
MeSH Terms
Bromodeoxyuridine
Chromosomes, Human, 21-22 and Y
Chromosomes, Human, 6-12 and X
Face/abnormalities
Female
Growth Disorders/genetics
Humans
Hypocalcemia/genetics
Infant
Infant, Newborn
Karyotyping
Pedigree
Psychomotor Disorders/genetics
Sex Chromosome Aberrations/diagnosis
Translocation, Genetic
X Chromosome
Chemicals
Bromodeoxyuridine
Authors & Affiliations
5 authors, click to expand affiliations / ORCID
Mattei M G
Mattei J F
Ayme S
Malpuech G
Giraud F
References (10)
10 references, click to expand
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