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PMID: 8577759 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Lens complementation system for the genetic analysis of growth, differentiation, and apoptosis in vivo.

Liégeois NJ, Horner JW, DePinho RA

Abstract

A genetic approach has been established that combines the advantages of blastocyst complementation with the experimental attributes of the developing lens for the functional analysis of genes governing cellular proliferation, terminal differentiation, and apoptosis. This lens complementation system (LCS) makes use of a mutant mouse strain, aphakia (ak), homozygotes of which fail to develop an ocular lens. We demonstrate that microinjection of wild-type embryonic stem (ES) cells into ak/ak blastocysts produces chimeras with normal ES-cell-derived lenses and that microinjection of Rb-/- ES cells generates an aberrant lens phenotype identical to that obtained through conventional gene targeting methodology. Our determination that a cell autonomous defect underlies the aphakia condition assures that lenses generated through LCS are necessarily ES-cell-derived. LCS provides for the rapid phenotypic analysis of loss-of-function mutations, circumvents the need for germ-line transmission of null alleles, and, most significantly, facilitates the study of essential genes whose inactivation is associated with early lethal phenotypes.

MeSH Terms
Animals Aphakia/embryology,genetics Apoptosis Blastocyst/cytology,physiology Cell Differentiation Cell Division Cell Line Crosses, Genetic Embryonic and Fetal Development Female Genetic Complementation Test Homozygote Lens, Crystalline/cytology,embryology,physiology Male Mice Mice, Mutant Strains Stem Cells/cytology,physiology
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Liégeois N J
Department of Microbiology, Albert Einstein College of Medicine, Bronx, NY 10461, USA.
Horner J W
DePinho R A
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21 references, click to expand
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Article Info
Journal
Proceedings of the National Academy of Sciences of the United States of America
Abbr.
Proc Natl Acad Sci U S A
ISSN
0027-8424
Published
1996-02-06
Pages
1303-7
Language
English
Region
United States
NLM ID
7505876
PMCID
PMC40075
Subset
IM
Grants
NCI NIH HHS · 2P30CA13330 · United States
NEI NIH HHS · EY09300 · United States
NIGMS NIH HHS · T32GM07288 · United States
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