Abstract
We report a constitutional point mutation of codon 278 in exon 8 of the TP53 gene that has not yet been described as a germ-line mutation. A 52-year-old female developed multiple primary malignancies (liposarcoma, breast cancer, malignant histiocytoma, occult adenocarcinoma). The mutation found in her tumour and peripheral blood lymphocyte DNA is a cytosine to thymine transition at the second position of codon 278 resulting in an amino acid exchange from proline to leucine in the DNA-binding domain. Evaluation of the patient's family revealed that both of her sons were affected by the same mutation. Although the patient's mother had died already, we were able to demonstrate by polymorphic microsatellite analysis that the defective allele originated from the maternal side. As four brothers and one sister had inherited the same allele, which however was wild type, we were able to show that the mutation must have occurred in the germ cells of the patient's mother and that it may therefore be called de novo. This explains the lack of a high cancer incidence in the family history. All tumours tested showed positive immunohistochemical staining for p53. Loss of heterozygosity was found in five of seven tumours, one showing chromosome 17 monosomy.
MeSH Terms
Alleles
Base Sequence
DNA, Neoplasm/analysis,genetics
DNA, Satellite/analysis,genetics
Exons
Family Health
Female
Gene Deletion
Genes, p53
Germ-Line Mutation
Haplotypes
Heterozygote
Humans
Immunohistochemistry
In Situ Hybridization, Fluorescence
Male
Middle Aged
Molecular Sequence Data
Neoplasms, Multiple Primary/genetics
Pedigree
Point Mutation
Polymorphism, Genetic
Tumor Suppressor Protein p53/analysis
Chemicals
DNA, Neoplasm
DNA, Satellite
Tumor Suppressor Protein p53
Authors & Affiliations
11 authors, click to expand affiliations / ORCID
Speiser P
University Hospital Vienna, Medical School, Department of Obstetrics and Gynecology, Austria.
Gharehbaghi-Schnell E
Eder S
Haid A
Kovarík J
Nenutil R
Sauter G
Schneeberger C H
Vojtesek B
Wiltschke C H
Zeillinger R
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