Abstract
The CAG repeat number in the Huntington's disease (HD) gene accounts for about 50% of the variation seen in age at onset of HD. In order to determine whether promoter sequence variation can contribute to the residual variation in age at onset, we studied the conserved 303 bp region upstream of the +1 translation start site in the HD gene in a population of 56 control East Anglians, 30 Africans, 34 Japanese, and 208 English Huntington's disease patients. A surprisingly high degree of variation was found. Seven alleles were identified, comprising four polymorphisms: two single base pair substitutions, a 6 bp VNTR present as one or two copies, and a 20 bp VNTR with one to three copies of the tandem repeat. No correlation between polymorphisms and age at onset of symptoms was found in HD patients. The 6 bp and 20 bp stretches are present only in single copies in the chimpanzees and gorilla, suggesting that these VNTRs have evolved by duplication of the core sequences in the human lineage.
MeSH Terms
Age of Onset
Alleles
Animals
Base Sequence
Gene Frequency
Genes/genetics
Humans
Huntington Disease/epidemiology,genetics
Molecular Sequence Data
Nucleic Acid Heteroduplexes/analysis
Point Mutation/genetics
Polymorphism, Single-Stranded Conformational
Repetitive Sequences, Nucleic Acid
Sequence Analysis, DNA
Trinucleotide Repeats
Chemicals
Nucleic Acid Heteroduplexes
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Coles R
Department of Pathology, Cambridge University, UK.
Leggo J
Rubinsztein D C
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