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PMID: 9152833 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't

Analysis of the 5' upstream sequence of the Huntington's disease (HD) gene shows six new rare alleles which are unrelated to the age at onset of HD.

Journal of medical genetics ·Vol. 34 ·No. 5 ·1997-05-00 ·Pages 371-4

Coles R, Leggo J, Rubinsztein DC

Abstract

The CAG repeat number in the Huntington's disease (HD) gene accounts for about 50% of the variation seen in age at onset of HD. In order to determine whether promoter sequence variation can contribute to the residual variation in age at onset, we studied the conserved 303 bp region upstream of the +1 translation start site in the HD gene in a population of 56 control East Anglians, 30 Africans, 34 Japanese, and 208 English Huntington's disease patients. A surprisingly high degree of variation was found. Seven alleles were identified, comprising four polymorphisms: two single base pair substitutions, a 6 bp VNTR present as one or two copies, and a 20 bp VNTR with one to three copies of the tandem repeat. No correlation between polymorphisms and age at onset of symptoms was found in HD patients. The 6 bp and 20 bp stretches are present only in single copies in the chimpanzees and gorilla, suggesting that these VNTRs have evolved by duplication of the core sequences in the human lineage.

MeSH Terms
Age of Onset Alleles Animals Base Sequence Gene Frequency Genes/genetics Humans Huntington Disease/epidemiology,genetics Molecular Sequence Data Nucleic Acid Heteroduplexes/analysis Point Mutation/genetics Polymorphism, Single-Stranded Conformational Repetitive Sequences, Nucleic Acid Sequence Analysis, DNA Trinucleotide Repeats
Chemicals
Nucleic Acid Heteroduplexes
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Coles R
Department of Pathology, Cambridge University, UK.
Leggo J
Rubinsztein D C
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19 references, click to expand
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Article Info
Journal
Journal of medical genetics
Abbr.
J Med Genet
ISSN
0022-2593
Published
1997-05-00
Pages
371-4
Language
English
Region
England
NLM ID
2985087R
PMCID
PMC1050943
Subset
IM
Grants
Wellcome Trust · United Kingdom
Databases
GENBANK
Y07981, Y07982, Y07983, Y07984, Y07985, Y07986, Y07987, Y07988, Y07989, Y07990
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