Home LiteratureArticle Details
PMID: 9389733 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Hepatic fibrosis, glomerulosclerosis, and a lipodystrophy-like syndrome in PEPCK-TGF-beta1 transgenic mice.

The Journal of clinical investigation ·Vol. 100 ·No. 11 ·1997-12-01 ·Pages 2697-713

Clouthier DE, Comerford SA, Hammer RE

Abstract

Transgenic mice overexpressing a constitutively active human TGF-beta1 under control of the rat phosphoenolpyruvate carboxykinase regulatory sequences developed fibrosis of the liver, kidney, and adipose tissue, and exhibited a severe reduction in body fat. Expression of the transgene in hepatocytes resulted in increased collagen deposition, altered lobular organization, increased hepatocyte turnover, and in extreme cases, hemorrhage and thrombosis. Renal expression of the transgene was localized to the proximal tubule epithelium, and was associated with tubulointerstitial fibrosis, characterized by excessive collagen deposition and increased fibronectin and plasminogen activator inhibitor-1 immunoreactivity. Pronounced glomerulosclerosis was evident, and hydronephrosis developed with low penetrance. Expression of TGF-beta1 in white and brown adipose tissue resulted in a lipodystrophy-like syndrome. All white fat depots and brown fat pads were severely reduced in size, and exhibited prominent fibroplasia. This reduction in WAT was due to impaired adipose accretion. Introduction of the transgene into the ob/ob background suppressed the obesity characteristic of this mutation; however, transgenic mutant mice developed severe hepato- and splenomegaly. These studies strengthen the link between TGF-beta1 expression and fibrotic disease, and demonstrate the potency of TGF-beta1 in modulating mesenchymal cell differentiation in vivo.

MeSH Terms
Adipose Tissue/metabolism Alanine Transaminase/metabolism Animals Apoptosis Aspartate Aminotransferases/metabolism Collagen/metabolism DNA/metabolism Female Glomerulosclerosis, Focal Segmental/etiology Humans Kidney/metabolism,pathology Lipodystrophy/etiology Liver/metabolism,pathology Liver Cirrhosis, Experimental/etiology Male Mice Mice, Inbred C57BL Mice, Obese Mice, Transgenic Phosphoenolpyruvate Carboxykinase (GTP)/biosynthesis,genetics,physiology Rats Recombinant Fusion Proteins Skin/metabolism,pathology Syndrome Transforming Growth Factor beta/biosynthesis,genetics,physiology
Chemicals
Recombinant Fusion Proteins Transforming Growth Factor beta Collagen DNA Aspartate Aminotransferases Alanine Transaminase Phosphoenolpyruvate Carboxykinase (GTP)
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Clouthier D E
Department of Biochemistry and the Howard Hughes Medical Institute, University of Texas Southwestern Medical Center, Dallas, Texas 75235-9050, USA.
Comerford S A
Hammer R E
References (60)
60 references, click to expand
  1. Transforming growth factor-beta is a renin secretagogue at picomolar concentrations.
    Am J Physiol. 1993 Oct;265(4 Pt 2):F537-41 PMID: 8238382
  2. Modulation of adipocyte differentiation by tumor necrosis factor and transforming growth factor beta.
    J Cell Biol. 1989 Mar;108(3):1105-13 PMID: 2921280
  3. TGF beta 1 prevents the down-regulation of type I procollagen, fibronectin, and TGF beta 1 gene expression associated with 3T3-L1 pre-adipocyte differentiation.
    J Cell Biochem. 1994 Feb;54(2):256-63 PMID: 8175900
  4. Angiotensin II stimulates extracellular matrix protein synthesis through induction of transforming growth factor-beta expression in rat glomerular mesangial cells.
    J Clin Invest. 1994 Jun;93(6):2431-7 PMID: 8200978
  5. Transforming growth factor-beta in glomerular injury.
    Exp Nephrol. 1994 Jan-Feb;2(1):13-7 PMID: 8081992
  6. Transforming growth factor beta in tissue fibrosis.
    N Engl J Med. 1994 Nov 10;331(19):1286-92 PMID: 7935686
  7. Positional cloning of the mouse obese gene and its human homologue.
    Nature. 1994 Dec 1;372(6505):425-32 PMID: 7984236
  8. Hepatic expression of mature transforming growth factor beta 1 in transgenic mice results in multiple tissue lesions.
    Proc Natl Acad Sci U S A. 1995 Mar 28;92(7):2572-6 PMID: 7708687
  9. Mammalian antiproliferative signals and their targets.
    Curr Opin Genet Dev. 1995 Feb;5(1):91-6 PMID: 7749332
  10. Transforming growth factor-beta and angiotensin II: the missing link from glomerular hyperfiltration to glomerulosclerosis?
    Annu Rev Physiol. 1995;57:279-95 PMID: 7778869
  11. Transcriptional regulation of gene expression during adipocyte differentiation.
    Annu Rev Biochem. 1995;64:345-73 PMID: 7574486
  12. Cell death in health and disease: the biology and regulation of apoptosis.
    Semin Cancer Biol. 1995 Feb;6(1):3-16 PMID: 7548839
  13. Targeted mutation in the Fas gene causes hyperplasia in peripheral lymphoid organs and liver.
    Nat Genet. 1995 Nov;11(3):294-300 PMID: 7581453
  14. Molecular mechanisms of liver fibrogenesis--a homage to the role of activated fat-storing cells.
    Digestion. 1995;56(5):335-46 PMID: 8549875
  15. Targeted in vivo expression of the cyclin-dependent kinase inhibitor p21 halts hepatocyte cell-cycle progression, postnatal liver development and regeneration.
    Genes Dev. 1996 Feb 1;10(3):245-60 PMID: 8595876
  16. Isolation of biologically active ribonucleic acid from sources enriched in ribonuclease.
    Biochemistry. 1979 Nov 27;18(24):5294-9 PMID: 518835
  17. A simple, rapid, and sensitive DNA assay procedure.
    Anal Biochem. 1980 Mar 1;102(2):344-52 PMID: 6158890
  18. Fibronectin modulation of cell shape and lipogenic gene expression in 3T3-adipocytes.
    Cell. 1983 Dec;35(3 Pt 2):657-66 PMID: 6686086
  19. Type beta transforming growth factor controls the adipogenic differentiation of 3T3 fibroblasts.
    Proc Natl Acad Sci U S A. 1985 Dec;82(24):8530-4 PMID: 3001708
  20. Hepatic lipocytes: the principal collagen-producing cells of normal rat liver.
    Proc Natl Acad Sci U S A. 1985 Dec;82(24):8681-5 PMID: 3909149
  21. A simple method for site-directed mutagenesis using the polymerase chain reaction.
    Nucleic Acids Res. 1989 Aug 25;17(16):6545-51 PMID: 2674899
  22. Fibroblast growth factor and transforming growth factor beta repress transcription of the myogenic regulatory gene MyoD1.
    Mol Cell Biol. 1989 Aug;9(8):3576-9 PMID: 2797000
  23. Immunohistochemical localization of phosphoenolpyruvate carboxykinase in adult and developing mouse tissues.
    J Histochem Cytochem. 1990 Feb;38(2):171-8 PMID: 1688895
  24. Cell adhesion to collagen and decreased myogenic gene expression implicated in the control of myogenesis by transforming growth factor beta.
    J Biol Chem. 1990 Jun 25;265(18):10181-4 PMID: 2162338
  25. Transient inhibition of liver regeneration in mice by transforming growth factor-beta 1 encapsulated in liposomes.
    Cancer Commun. 1990;2(5):165-71 PMID: 2369553
  26. Suppression of experimental glomerulonephritis by antiserum against transforming growth factor beta 1.
    Nature. 1990 Jul 26;346(6282):371-4 PMID: 2374609
  27. Predominant periportal expression of the phosphoenolpyruvate carboxykinase and tyrosine aminotransferase genes in rat liver. Dynamics during the daily feeding rhythm and starvation-refeeding cycle demonstrated by in situ hybridization.
    Histochemistry. 1990;94(6):637-44 PMID: 1980679
  28. Transforming growth factors beta 1 and alpha in chronic liver disease. Effects of interferon alfa therapy.
    N Engl J Med. 1991 Apr 4;324(14):933-40 PMID: 1900574
  29. Liver tumor promotion: effect of phenobarbital on EGF and protein kinase C signal transduction and transforming growth factor-beta 1 expression.
    Dig Dis Sci. 1991 May;36(5):659-68 PMID: 2022168
  30. Transforming growth factor beta represses the actions of myogenin through a mechanism independent of DNA binding.
    Proc Natl Acad Sci U S A. 1991 May 1;88(9):3822-6 PMID: 1850837
  31. Effects of TGF-beta s in the liver: cell proliferation and fibrogenesis.
    Ciba Found Symp. 1991;157:165-74; discussion 174-7 PMID: 1649033
  32. Abnormal brown and white fat development in transgenic mice overexpressing glycerol 3-phosphate dehydrogenase.
    Genes Dev. 1991 Dec;5(12A):2256-64 PMID: 1748283
  33. TGF-beta blocks early but not late differentiation-specific gene expression and morphologic differentiation of 3T3 T proadipocytes.
    J Cell Physiol. 1992 Mar;150(3):568-77 PMID: 1537885
  34. Tissue-specific, developmental, hormonal, and dietary regulation of rat phosphoenolpyruvate carboxykinase-human growth hormone fusion genes in transgenic mice.
    Mol Cell Biol. 1992 Mar;12(3):1007-20 PMID: 1545785
  35. Induction of apoptosis in cultured hepatocytes and in regressing liver by transforming growth factor beta 1.
    Proc Natl Acad Sci U S A. 1992 Jun 15;89(12):5408-12 PMID: 1608949
  36. Tubulointerstitial changes as a major determinant in the progression of renal damage.
    Am J Kidney Dis. 1992 Jul;20(1):1-17 PMID: 1621674
  37. Transforming growth factor-beta in disease: the dark side of tissue repair.
    J Clin Invest. 1992 Jul;90(1):1-7 PMID: 1634602
  38. Renal growth factor expression during the early phase of experimental hydronephrosis.
    J Urol. 1992 Aug;148(2 Pt 2):510-4 PMID: 1640512
  39. Cellular and molecular aspects of adipose tissue development.
    Annu Rev Nutr. 1992;12:207-33 PMID: 1503804
  40. Identification of programmed cell death in situ via specific labeling of nuclear DNA fragmentation.
    J Cell Biol. 1992 Nov;119(3):493-501 PMID: 1400587
  41. Targeted disruption of the mouse transforming growth factor-beta 1 gene results in multifocal inflammatory disease.
    Nature. 1992 Oct 22;359(6397):693-9 PMID: 1436033
  42. Natural inhibitor of transforming growth factor-beta protects against scarring in experimental kidney disease.
    Nature. 1992 Nov 26;360(6402):361-4 PMID: 1280332
  43. Glomerular matrix accumulation is linked to inhibition of the plasmin protease system.
    Kidney Int. 1992 Dec;42(6):1462-9 PMID: 1474781
  44. Transforming growth factor beta 1 null mutation in mice causes excessive inflammatory response and early death.
    Proc Natl Acad Sci U S A. 1993 Jan 15;90(2):770-4 PMID: 8421714
  45. Susceptibility to inflammatory disease in HLA-B27 transgenic rat lines correlates with the level of B27 expression.
    J Immunol. 1993 May 1;150(9):4168-78 PMID: 8473755
  46. Regulation of extracellular matrix synthesis by transforming growth factor beta 1 in human fat-storing cells.
    Gastroenterology. 1993 Jul;105(1):245-53 PMID: 8514041
  47. Dysfunction of glomerular fibrinolysis in experimental antiglomerular basement membrane antibody glomerulonephritis.
    J Am Soc Nephrol. 1993 May;3(11):1753-64 PMID: 8329670
  48. Regulation of adipose maturation and energy homeostasis.
    Curr Opin Cell Biol. 1995 Dec;7(6):885-90 PMID: 8608020
  49. Transgenic mice with increased plasma levels of TGF-beta 1 develop progressive renal disease.
    Lab Invest. 1996 Jun;74(6):991-1003 PMID: 8667617
  50. TGFbeta signaling: receptors, transducers, and Mad proteins.
    Cell. 1996 Jun 28;85(7):947-50 PMID: 8674122
  51. Signaling via hetero-oligomeric complexes of type I and type II serine/threonine kinase receptors.
    Curr Opin Cell Biol. 1996 Apr;8(2):139-45 PMID: 8791413
  52. Inhibition of TGF-beta 1 expression by antisense oligonucleotides suppressed extracellular matrix accumulation in experimental glomerulonephritis.
    Kidney Int. 1996 Jul;50(1):148-55 PMID: 8807583
  53. MAD-related proteins in TGF-beta signalling.
    Trends Genet. 1996 Dec;12(12):493-6 PMID: 9257525
  54. Replacement of insulin receptor tyrosine residues 1162 and 1163 compromises insulin-stimulated kinase activity and uptake of 2-deoxyglucose.
    Cell. 1986 Jun 6;45(5):721-32 PMID: 3518947
  55. Transforming growth factor type beta is a specific inhibitor of 3T3 T mesenchymal stem cell differentiation.
    Exp Cell Res. 1986 Aug;165(2):345-52 PMID: 3459667
  56. Type beta transforming growth factor is an inhibitor of myogenic differentiation.
    Proc Natl Acad Sci U S A. 1986 Nov;83(21):8206-10 PMID: 3022285
  57. Human transforming growth factor type beta 2: production by a prostatic adenocarcinoma cell line, purification, and initial characterization.
    Biochemistry. 1987 May 5;26(9):2406-10 PMID: 3475130
  58. Transforming growth factor-beta: potential common mechanisms mediating its effects on embryogenesis, inflammation-repair, and carcinogenesis.
    Int J Rad Appl Instrum B. 1987;14(4):435-9 PMID: 3308784
  59. Type beta transforming growth factor reversibly inhibits the early proliferative response to partial hepatectomy in the rat.
    Proc Natl Acad Sci U S A. 1988 Jul;85(14):5126-30 PMID: 3164865
  60. The TGF-beta superfamily: new members, new receptors, and new genetic tests of function in different organisms.
    Genes Dev. 1994 Jan;8(2):133-46 PMID: 8299934
Article Info
Journal
The Journal of clinical investigation
Abbr.
J Clin Invest
ISSN
0021-9738
Published
1997-12-01
Pages
2697-713
Language
English
Region
United States
NLM ID
7802877
PMCID
PMC508473
Subset
IM
Grants
NIAID NIH HHS · AI28332-01 · United States
NIDDK NIH HHS · DK09376-01 · United States
Analysis Services
Analysis Services

Contact

No. 2 Wenbo Road, Zhangqiu District, Jinan, Shandong

Qilu Normal University · Genelibs Bioinformatics Lab

750 Shunhua Rd, Jinan

2F, Bldg F, University Science Park

Tel: 0531-88819269

WeChat Official Account

Follow our WeChat subscription account for real-time updates and the latest in medical and biological research.


Business Email

E-mail: [email protected]