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PMID: 984047 Published · ppublish English Journal Article Research Support, U.S. Gov't, P.H.S.

The physicochemical properties of hair in the BIDS syndrome.

American journal of human genetics ·Vol. 28 ·No. 5 ·1976-09-00 ·Pages 514-21

Baden HP, Jackson CE, Weiss L, Jimbow K, Lee L, Kubilus J, Gold RJ

Abstract

The physicochemical properties of hair from a new recessive syndrome associated with brittle hair, intellectual impairment, decreased fertility, and short stature have been studied. Electrophoresis of the SCM-structural proteins showed that the alpha polypeptides appeared normal, but the matrix component was markedly reduced. This was confirmed by finding a normal alpha X-ray diffraction pattern but a reduced 1/2 cystine content of hair and an abnormal stress-strain curve. Electron-microscopic studies revealed extreme disorganization of the filaments which most likely resulted from the absence of normal cross-linking. Nails, which contain structural proteins similar to hair, also showed the abnormality. Since the matrix component seen by electrophoresis consists of more than one component the defect cannot be explained as a single structural gene abnormality.

MeSH Terms
Amino Acids/analysis Female Genes, Recessive Growth Disorders Hair/abnormalities,analysis,ultrastructure Humans Infertility Intellectual Disability Male Microscopy, Electron Nails/analysis,ultrastructure Proteins/analysis Syndrome
Chemicals
Amino Acids Proteins
Authors & Affiliations
7 authors, click to expand affiliations / ORCID
Baden H P
Jackson C E
Weiss L
Jimbow K
Lee L
Kubilus J
Gold R J
References (9)
9 references, click to expand
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Article Info
Journal
American journal of human genetics
Abbr.
Am J Hum Genet
ISSN
0002-9297
Published
1976-09-00
Pages
514-21
Language
English
Region
United States
NLM ID
0370475
PMCID
PMC1685097
Subset
IM
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