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PMID: 18065781 Published · ppublish English Comparative Study Journal Article Research Support, N.I.H., Extramural

Sex-dependent association of a common low-density lipoprotein receptor polymorphism with RNA splicing efficiency in the brain and Alzheimer's disease.

Human molecular genetics ·Vol. 17 ·No. 7 ·2008-04-01 ·Pages 929-35

Zou F, Gopalraj RK, Lok J, Zhu H, Ling IF, Simpson JF, Tucker HM, Kelly JF, Younkin SG, Dickson DW, Petersen RC, Graff-Radford NR, Bennett DA, Crook JE, Younkin SG, Estus S

Abstract

Since apoE allele status is the predominant Alzheimer's disease (AD) genetic risk factor, functional single nucleotide polymorphisms (SNPs) in brain apoE receptors represent excellent candidates for association with AD. Recently, we identified a SNP, rs688, as modulating the splicing efficiency of low-density lipoprotein receptor (LDLR) exon 12 in female human liver and in minigene-transfected HepG2 cells. Moreover, the rs688T minor allele was associated with significantly higher LDL and total cholesterol in women within the Framingham Offspring Study cohort. Since LDLR is a major apoE receptor in the brain, we hypothesized that rs688 modulates LDLR splicing in neural tissues and associates with AD. To evaluate this hypothesis, we first transfected LDLR minigenes into SH-SY5Y neuroblastoma cells and found that the rs688T allele reduces exon 12 inclusion in this neural model. We then evaluated the association of rs688 allele with exon 12 splicing efficiency in vivo by quantifying LDLR splicing in human anterior cingulate tissue obtained at autopsy; the rs688T allele is associated with decreased LDLR exon 12 splicing efficiency in aged males, but not females. Lastly, we evaluated whether rs688 associates with AD by genotyping DNA from 1457 men and 2055 women drawn from three case-control series. The rs688T/T genotype was associated with increased AD odds in males [recessive model, odds ratio (OR) of 1.49, 95% confidence interval (CI) of 1.13-1.97, uncorrected P = 0.005], but not in females. In summary, these studies identify a functional apoE receptor SNP that is associated with AD in a sex-dependent fashion.

MeSH Terms
Aged Aged, 80 and over Alzheimer Disease/genetics,metabolism Apolipoproteins E/metabolism Brain/metabolism Case-Control Studies Cell Line, Tumor Exons Female Humans Male Mutagenesis, Site-Directed Odds Ratio Polymorphism, Single Nucleotide RNA Splicing Receptors, LDL/genetics Reverse Transcriptase Polymerase Chain Reaction Sex Characteristics
Chemicals
Apolipoproteins E Receptors, LDL
Authors & Affiliations
16 authors, click to expand affiliations / ORCID
Zou Fanggeng
Department of Neuroscience, Mayo Clinic, 4500 San Pablo Road, Jacksonville, FL 32224, USA.
Gopalraj Rangaraj K
Lok Johann
Zhu Haiyan
Ling I-Fang
Simpson James F
Tucker H Michael
Kelly Jeremiah F
Younkin Samuel G
Dickson Dennis W
Petersen Ronald C
Graff-Radford Neill R
Bennett David A
Crook Julia E
Younkin Steven G
Estus Steven
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Article Info
Journal
Human molecular genetics
Abbr.
Hum Mol Genet
ISSN
1460-2083
Published
2008-04-01
Epub
2007-00-08
Pages
929-35
Language
English
Region
England
NLM ID
9208958
PMCID
PMC2361153
Subset
IM
Grants
NIA NIH HHS · P30AG028383 · United States
NIA NIH HHS · P50 AG016574 · United States
NIA NIH HHS · R01 AG026147-01A2 · United States
NIA NIH HHS · R01AG026147 · United States
NIA NIH HHS · R01 AG026147 · United States
NIA NIH HHS · R01AG15819 · United States
NIA NIH HHS · P30AG10161 · United States
NIA NIH HHS · AG16574 · United States
NIA NIH HHS · P30 AG028383 · United States
NIA NIH HHS · R01 AG015819 · United States
NIA NIH HHS · P30 AG010161 · United States
NIA NIH HHS · P01 AG030128 · United States
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