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PMID: 2011523 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't

Different mechanisms inferred from sequences of human mitochondrial DNA deletions in ocular myopathies.

Nucleic acids research ·Vol. 19 ·No. 3 ·1991-02-11 ·Pages 493-6

Degoul F, Nelson I, Amselem S, Romero N, Obermaier-Kusser B, Ponsot G, Marsac C, Lestienne P

Abstract

We have sequenced the deletion borders of the muscle mitochondrial DNA from 24 patients with heteroplasmic deletions. The length of these deletions varies from 2.310 bp to 8.476 bp and spans from position 5.786 to 15.925 of the human mitochondrial genome preserving the heavy chain and light chain origins of replication. 12 cases are common deletions identical to the mutation already described by other workers and characterized by 13 bp repeats at the deletion boundaries, one of these repeats being retained during the deletion process. The other cases (10 out of 12) have shown deletions which have not been previously described. All these deletions are located in the H strand DNA region which is potentially single stranded during mitochondrial DNA replication. In two cases, the retained Adenosine from repeat closed to the heavy strand origin of replication would indicate slippage mispairing. Furthermore in one patient two mt DNA molecules have been cloned and their sequences showed the difference of four nucleotides in the breakpoint of the deletion, possibly dued to slippage mispairing. Taken together our results suggest that deletions occur either by slippage mispairing or by internal recombination at the direct repeat level. They also suggest that different mechanisms account for the deletions since similarly located deletions may display different motives at the boundaries including the absence of any direct repeat.

MeSH Terms
Base Sequence DNA, Mitochondrial/genetics Eye Diseases/genetics Humans Mitochondria, Muscle/chemistry Molecular Sequence Data Mutation Polymerase Chain Reaction Recombination, Genetic
Chemicals
DNA, Mitochondrial
Authors & Affiliations
8 authors, click to expand affiliations / ORCID
Degoul F
Inserm U 75, Faculté de médecine Necker-Enfants Malades, Paris, FRG.
Nelson I
Amselem S
Romero N
Obermaier-Kusser B
Ponsot G
Marsac C
Lestienne P
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Article Info
Journal
Nucleic acids research
Abbr.
Nucleic Acids Res
ISSN
0305-1048
Published
1991-02-11
Pages
493-6
Language
English
Region
England
NLM ID
0411011
PMCID
PMC333638
Subset
IM
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