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PMID: 3122181 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

A novel missense mutation in the factor VIII gene identified by analysis of amplified hemophilia DNA sequences.

Nucleic acids research ·Vol. 15 ·No. 23 ·1987-12-10 ·Pages 9797-805

Levinson B, Janco R, Phillips J, Gitschier J

Abstract

To date the only point mutations demonstrated to cause hemophilia are C to T transitions in TaqI sites. These were detected by screening Southern blots with cloned factor VIII probes. During the development of improved methods for detecting and analyzing mutations in genomic DNA, a novel G to C transversion mutation has been identified. This rare transversion results in a missense mutation, with proline being substituted for arginine in one of the active domains of the factor VIII molecule. The results suggest that the improved methods will be useful for detecting mutations in hemophilia as well as in other genetic disorders. In this method, specific DNA sequences in genomic DNA are amplified using oligonucleotide primers and a heat-resistant DNA polymerase. Mutations are detected and localized in the amplified samples by RNase A cleavage, and the altered region is then sequenced.

MeSH Terms
Base Sequence Cloning, Molecular DNA Mutational Analysis/methods Factor VIII/genetics Gene Amplification Hemophilia A/blood,genetics Humans Male Ribonucleases/genetics
Chemicals
Factor VIII Ribonucleases
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Levinson B
Howard Hughes Medical Institute, Department of Medicine, San Francisco, CA 94143.
Janco R
Phillips J
Gitschier J
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Article Info
Journal
Nucleic acids research
Abbr.
Nucleic Acids Res
ISSN
0305-1048
Published
1987-12-10
Pages
9797-805
Language
English
Region
England
NLM ID
0411011
PMCID
PMC306532
Subset
IM
Grants
NHLBI NIH HHS · HL35097 · United States
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