Home LiteratureArticle Details
PMID: 4982231 Published · ppublish English Journal Article

Immunochemical studies in four cases of alpha chain disease.

The Journal of clinical investigation ·Vol. 48 ·No. 12 ·1969-12-00 ·Pages 2374-89

Seligmann M, Mihaesco E, Hurez D, Mihaesco C, Preud'homme JL, Rambaud JC

Abstract

Studies of a number of properties of the pathological gammaA-proteins in the first four cases of the recently recognized alpha-chain disease demonstrate that, as in gamma-heavy-chain disease, the abnormal protein is devoid of light chains and represents a portion of the alpha-heavy chain related to the Fc-fragment. In two patients, serum electrophoresis showed a broad abnormal band, whereas in the two others the pathological protein was not noticeable on the electrophoretic pattern. The diagnosis of alpha-chain disease can be established without purification of the protein by immuno-electrophoresis and gel diffusion experiments using selected antisera to gammaA and a reference alpha-chain disease protein. All four proteins belonged to the alpha1-subclass, displayed electrophoretic heterogeneity, and showed a strong tendency to polymerize. The polymers occurred in vivo and were held together both by disulfide bonds and by strong noncovalent forces. Two of the three purified proteins had a very high carbohydrate content. The abnormal protein was always found in concentrated urines in variable but generally low amounts. It was not detected in parotid saliva but was present in significant amounts in jejunal fluid of all four patients. The alpha-chain disease protein was shown to be associated with the secretory piece in external secretions of two patients. The clinicopathological features were strikingly similar in the four patients. All patients were affected with a neoplastic and mostly plasmacytic proliferation involving primarily the whole length of the small intestine and the mesenteric nodes and all exhibited a severe malabsorption syndrome. While Israeli authors have emphasized the frequency of this type of abdominal lymphoma in young Arabs and non-Ashkenazi Jews, two of our patients were Kabyles, one a Syrian Arab, and one an Eurasian. Cellular studies showed that the pathological protein was synthesized by the proliferating cells in the lymphoid tissue of the digestive tract and in the mesenteric nodes, and that there was no detectable light-chain synthesis at the intracellular level.

MeSH Terms
Blood Protein Disorders/immunology Blood Protein Electrophoresis Chromatography, Gel Fluorescent Antibody Technique Fucose/analysis Hexosamines/analysis Hexoses/analysis Humans Immunochemistry Immunodiffusion Immunoelectrophoresis Intestinal Neoplasms Intestine, Small/pathology Jejunum/analysis Lymphoma Malabsorption Syndromes Neuraminic Acids/analysis Proteinuria Racial Groups Saliva/analysis
Chemicals
Hexosamines Hexoses Neuraminic Acids Fucose
Authors & Affiliations
6 authors, click to expand affiliations / ORCID
Seligmann M
Mihaesco E
Hurez D
Mihaesco C
Preud'homme J L
Rambaud J C
References (35)
35 references, click to expand
  1. Specificity of recombination of H and L chains from human gamma-G-myeloma proteins.
    J Exp Med. 1965 Sep 1;122(3):619-32 PMID: 4158438
  2. A genetic predisposition to Waldenström's macroglobulinaemia.
    Acta Med Scand Suppl. 1966;445:140-6 PMID: 4160689
  3. Immunochemical quantitation of antigens by single radial immunodiffusion.
    Immunochemistry. 1965 Sep;2(3):235-54 PMID: 4956917
  4. [Immunohistochemical study of the plasmacytes of normal human intestinal mucosa].
    Rev Fr Etud Clin Biol. 1966 May;11(5):484-92 PMID: 4160939
  5. Multiple myeloma involving the gastrointestinal tract.
    Gastroenterology. 1966 Jul;51(1):87-93 PMID: 5939346
  6. Subclasses of human immunoglobulin a based on differences in the alpha polypeptide chains.
    Science. 1966 Aug 5;153(3736):647-9 PMID: 4161145
  7. Atypical antigenic properties of a gamma-A myeloma protein.
    J Immunol. 1966 May;96(5):842-8 PMID: 5913755
  8. Subgroups of gamma-A immune globulins.
    Proc Soc Exp Biol Med. 1966 Jul;122(3):910-3 PMID: 4162111
  9. Antigenic determinants common to human immunoglobulins G and M: importance of conformational antigens.
    Science. 1966 Nov 11;154(3750):790-1 PMID: 4162133
  10. Recombination of heavy and light chains of human gamma-a-myeloma proteins: formation of hybrid molecules and configurational specificity.
    J Exp Med. 1966 Aug 1;124(2):185-97 PMID: 4162153
  11. [Practical method of preparative electrophoresis in Pevikon sheets].
    Rev Fr Etud Clin Biol. 1967 Jun-Jul;12(6):608-11 PMID: 6049778
  12. [An unrecognized immunoglobinopathy: heavy chain disease].
    Presse Med. 1967 Oct 28;75(45):2251-4 PMID: 4167867
  13. N- and C-terminal sequences of a heavy chain disease protein and its genetic implications.
    Nature. 1967 Sep 23;215(5108):1386-7 PMID: 4168059
  14. Lymphoma presenting as malabsorption.
    Gastroenterology. 1968 Mar;54(3):421-5 PMID: 5643030
  15. Immunoglobulin content of intestinal mucosal plasma-cells in ataxia telangiectasia.
    Lancet. 1968 Apr 27;1(7548):884-6 PMID: 4171489
  16. Heavy-chain disease. Report of a seventh case.
    N Engl J Med. 1968 May 30;278(22):1195-201 PMID: 4172475
  17. [Importance of the molecular conformation in antigenic structure].
    Rev Fr Etud Clin Biol. 1967 Nov;12(9):851-4 PMID: 4173543
  18. Intractable watery diarrhea, hypokalemia, and malabsorption in a patient with Mediterranean type of abdominal lymphoma.
    Gastroenterology. 1968 Jul;55(1):118-24 PMID: 4874286
  19. [Separation of immunoglobulins density gradient ultracentrifugation].
    Rev Fr Etud Clin Biol. 1967 Nov;12(9):915-8 PMID: 4174270
  20. A subclass of human gamma-A-globulins (gamma-A2) which lacks the disulfied bonds linking heavy and light chains.
    J Exp Med. 1968 Dec 1;128(6):1223-36 PMID: 4176936
  21. Alpha-chain disease: a new immunoglobulin abnormality.
    Science. 1968 Dec 20;162(3860):1396-7 PMID: 4177362
  22. Clinico-pathological study of a patient with "Mediterranean" type of abdominal lymphoma and a new type of IgA abnormality ("alpha chain disease").
    Digestion. 1968;1(6):321-36 PMID: 5715198
  23. Biosynthetic and structural studies of a heavy chain disease protein.
    J Clin Invest. 1969 Apr;48(4):785-93 PMID: 4180120
  24. Immunoglobulin biosynthesis. 3. Blocks in defective synthesis.
    J Mol Biol. 1968 Dec;38(3):273-88 PMID: 4180613
  25. An immunofluorescence procedure for the detection of intracellular immunoglobulins.
    Clin Exp Immunol. 1969 Apr;4(4):457-72 PMID: 4182405
  26. Method for the determination of hexosamines in tissues.
    J Biol Chem. 1953 Oct;204(2):553-63 PMID: 13117829
  27. Analysis of hexose phosphates and sugar mixtures with the anthrone reagent.
    J Biol Chem. 1954 May;208(1):55-9 PMID: 13174514
  28. An improved procedure for starch-gel electrophoresis: further variations in the serum proteins of normal individuals.
    Biochem J. 1959 Mar;71(3):585-7 PMID: 13638269
  29. The thiobarbituric acid assay of sialic acids.
    J Biol Chem. 1959 Aug;234(8):1971-5 PMID: 13672998
  30. The use of urea-starch-gel electrophoresis in studies of reductive cleavage of an alpha 2-macroglobulin.
    Biochim Biophys Acta. 1960 Nov 4;44:390-3 PMID: 13737545
  31. Reduction of gamma-globulins.
    Arch Biochem Biophys. 1962 Sep;Suppl 1:174-80 PMID: 13945475
  32. HEAVY CHAIN DISEASE- A NEW DISORDER OF SERUM GAMMA-GLOBULINS : REPORT OF THE FIRST CASE.
    Am J Med. 1964 Sep;37:332-50 PMID: 14209281
  33. CLINICAL AND IMMUNOCHEMICAL STUDIES OF FOUR CASES OF HEAVY (H-GAMMA-2) CHAIN DISEASE.
    Am J Med. 1964 Sep;37:351-73 PMID: 14209282
  34. STRUCTURAL STUDIES OF HUMAN 7S GAMMA-GLOBULIN (G IMMUNOGLOBULIN). FURTHER OBSERVATIONS OF A NATURALLY OCCURRING PROTEIN RELATED TO THE CRYSTALLIZABLE (FAST) FRAGMENT.
    J Exp Med. 1964 Nov 1;120:691-709 PMID: 14247713
  35. MALABSORPTION SYNDROME IN LYMPHOMA OF SMALL INTESTINE. A STUDY OF 13 CASES.
    Isr J Med Sci. 1965 Mar;1:221-6 PMID: 14279068
Article Info
Journal
The Journal of clinical investigation
Abbr.
J Clin Invest
ISSN
0021-9738
Published
1969-12-00
Pages
2374-89
Language
English
Region
United States
NLM ID
7802877
PMCID
PMC297495
Subset
IM
Analysis Services
Analysis Services

Contact

No. 2 Wenbo Road, Zhangqiu District, Jinan, Shandong

Qilu Normal University · Genelibs Bioinformatics Lab

750 Shunhua Rd, Jinan

2F, Bldg F, University Science Park

Tel: 0531-88819269

WeChat Official Account

Follow our WeChat subscription account for real-time updates and the latest in medical and biological research.


Business Email

E-mail: [email protected]